Two Rare Vascular Rings With Ductal Origin of the Left Pulmonary Artery: A Previously Unrecognized Syndrome?

World J Pediatr Congenit Heart Surg. 2018 May;9(3):352-356. doi: 10.1177/2150135116675166. Epub 2016 Dec 6.

Abstract

We report two neonates with distal ductal origin of the left pulmonary artery who also had rare vascular rings comprised of a left aortic arch and right arterial duct with a midline/rightward descending aorta. To the best of our knowledge, this association has not previously been described, although other abnormalities of the left pulmonary artery in the setting of vascular rings have been reported. We review the embryology, utility of imaging, and clinical course.

Keywords: congenital heart disease; patent arterial duct; pulmonary artery abnormalities; vascular ring.

Publication types

  • Case Reports

MeSH terms

  • Fatal Outcome
  • Female
  • Humans
  • Infant, Newborn
  • Infant, Premature
  • Male
  • Pulmonary Artery / abnormalities*
  • Pulmonary Artery / diagnostic imaging
  • Syndrome
  • Vascular Malformations / diagnostic imaging*
  • Vascular Malformations / surgery
  • Vascular Ring / diagnostic imaging*
  • Vascular Ring / surgery