Case Report

J Child Neurol. 2017 Mar;32(4):403-407. doi: 10.1177/0883073816685508. Epub 2017 Jan 6.

Abstract

Glutaminyl-tRNA synthetase (QARS) deficiency has been described to be a cause of a neurodegenerative disorder associated with severe developmental delay, microcephaly, delayed myelination, and intractable epilepsy. The epilepsy is thought to be more severe than other tRNA synthetase disorders. Only a few cases have been reported in the literature and there is little information about response to different treatment options. The ketogenic diet is a high-fat, low-carbohydrate diet that is used in treatment resistant epilepsy of various etiologies. There are reports that the diet can also improve neuro-cognitive parameters. The authors report a case of a patient with glutaminyl-tRNA synthetase deficiency and treatment resistant seizures where there was a marked and early favorable response in terms of seizures, alertness and behavior to the ketogenic diet.

Keywords: antiseizure drugs; epilepsy; ketogenic diet; next-generation sequencing; refractory.

Publication types

  • Case Reports

MeSH terms

  • Amino Acyl-tRNA Synthetases / deficiency*
  • Brain / physiopathology
  • Child
  • Diet, Ketogenic*
  • Drug Resistant Epilepsy / diet therapy*
  • Drug Resistant Epilepsy / enzymology
  • Drug Resistant Epilepsy / psychology*
  • Electroencephalography
  • Humans
  • Male
  • Seizures / diet therapy*
  • Seizures / enzymology
  • Seizures / psychology*
  • Treatment Outcome

Substances

  • Amino Acyl-tRNA Synthetases
  • glutaminyl-tRNA synthetase