Human AML-iPSCs Reacquire Leukemic Properties after Differentiation and Model Clonal Variation of Disease

Cell Stem Cell. 2017 Mar 2;20(3):329-344.e7. doi: 10.1016/j.stem.2016.11.018. Epub 2017 Jan 12.

Abstract

Understanding the relative contributions of genetic and epigenetic abnormalities to acute myeloid leukemia (AML) should assist integrated design of targeted therapies. In this study, we generated induced pluripotent stem cells (iPSCs) from AML patient samples harboring MLL rearrangements and found that they retained leukemic mutations but reset leukemic DNA methylation/gene expression patterns. AML-iPSCs lacked leukemic potential, but when differentiated into hematopoietic cells, they reacquired the ability to give rise to leukemia in vivo and reestablished leukemic DNA methylation/gene expression patterns, including an aberrant MLL signature. Epigenetic reprogramming was therefore not sufficient to eliminate leukemic behavior. This approach also allowed us to study the properties of distinct AML subclones, including differential drug susceptibilities of KRAS mutant and wild-type cells, and predict relapse based on increased cytarabine resistance of a KRAS wild-type subclone. Overall, our findings illustrate the value of AML-iPSCs for investigating the mechanistic basis and clonal properties of human AML.

Keywords: MLL; acute myeloid leukemia; epigenetics; induced pluripotent stem cells; reprogramming.

Publication types

  • Research Support, N.I.H., Extramural
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Blast Crisis / pathology
  • Cell Differentiation*
  • Cell Line, Tumor
  • Cell Lineage
  • Cell Shape
  • Cellular Reprogramming
  • Chromosome Aberrations
  • Clone Cells
  • DNA Methylation / genetics
  • Epigenesis, Genetic
  • Gene Expression Profiling
  • Gene Expression Regulation, Leukemic
  • HEK293 Cells
  • Hematopoiesis / genetics
  • Humans
  • Induced Pluripotent Stem Cells / cytology*
  • Leukemia, Myeloid, Acute / genetics
  • Leukemia, Myeloid, Acute / pathology*
  • Models, Biological*
  • Molecular Targeted Therapy
  • Mutation / genetics
  • Neoplasm Invasiveness
  • Phenotype