Longitudinal analysis of treatment-induced genomic alterations in gliomas

Genome Med. 2017 Feb 2;9(1):12. doi: 10.1186/s13073-017-0401-9.

Abstract

Background: Glioblastoma multiforme (GBM) constitutes nearly half of all malignant brain tumors and has a median survival of 15 months. The standard treatment for these lesions includes maximal resection, radiotherapy, and chemotherapy; however, individual tumors display immense variability in their response to these approaches. Genomic techniques such as whole-exome sequencing (WES) provide an opportunity to understand the molecular basis of this variability.

Methods: Here, we report WES-guided treatment of a patient with a primary GBM and two subsequent recurrences, demonstrating the dynamic nature of treatment-induced molecular changes and their implications for clinical decision-making. We also analyze the Yale-Glioma cohort, composed of 110 whole exome- or whole genome-sequenced tumor-normal pairs, to assess the frequency of genomic events found in the presented case.

Results: Our longitudinal analysis revealed how the genomic profile evolved under the pressure of therapy. Specifically targeted approaches eradicated treatment-sensitive clones while enriching for resistant ones, generated due to chromothripsis, which we show to be a frequent event in GBMs based on our extended analysis of 110 gliomas in the Yale-Glioma cohort. Despite chromothripsis and the later acquired mismatch-repair deficiency, genomics-guided personalized treatment extended survival to over 5 years. Interestingly, the case displayed a favorable response to immune checkpoint inhibition after acquiring mismatch repair deficiency.

Conclusions: Our study demonstrates the importance of longitudinal genomic profiling to adjust to the dynamic nature of treatment-induced molecular changes to improve the outcomes of precision therapies.

Keywords: Genomics-guided precision medicine; Glioma; Immune checkpoint inhibition; Longitudinal genomic analysis; Mismatch repair deficiency; Tumor evolution.

Publication types

  • Case Reports
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Antineoplastic Agents / therapeutic use
  • Chromosome Aberrations*
  • Combined Modality Therapy
  • DNA Mismatch Repair
  • DNA Mutational Analysis
  • DNA, Neoplasm
  • Disease Progression
  • Exome
  • Female
  • General Surgery
  • Genome, Human
  • Genomics*
  • Glioblastoma / genetics
  • Glioblastoma / pathology
  • Glioblastoma / therapy*
  • Humans
  • Immunotherapy
  • Longitudinal Studies
  • Middle Aged
  • Mutation
  • Neoplasm Recurrence, Local*
  • Precision Medicine*
  • Radiotherapy
  • Treatment Outcome

Substances

  • Antineoplastic Agents
  • DNA, Neoplasm