Novel MCA/ID syndrome with ASH1L mutation

Am J Med Genet A. 2017 Jun;173(6):1644-1648. doi: 10.1002/ajmg.a.38193. Epub 2017 Apr 10.

Abstract

We identified a novel mutation in ASH1L in a patient with severe intellectual disability, growth failure, microcephaly, facial dysmorphism, myelination delay, and skeletal abnormalities. ASH1L is a histone methyltransferase that associates with the transcribed region of all active genes examined, including Hox genes. It catalyzes H3K36 methylation and plays important roles in development. There has been increasing evidence that heterozygous mutation of ASH1L is associated with ID and autism spectrum disorders. We suggest that ASH1L abnormalities may cause a novel MCA/ID syndrome.

Keywords: ASH1L; H3K36 methylation; intellectual disability; multiple congenital anomaly.

Publication types

  • Case Reports

MeSH terms

  • Child, Preschool
  • Congenital Abnormalities / diagnostic imaging
  • Congenital Abnormalities / genetics*
  • Congenital Abnormalities / physiopathology
  • DNA-Binding Proteins / genetics*
  • Histone-Lysine N-Methyltransferase
  • Humans
  • Intellectual Disability / diagnostic imaging
  • Intellectual Disability / genetics*
  • Intellectual Disability / physiopathology
  • Magnetic Resonance Imaging
  • Male
  • Microcephaly / genetics
  • Microcephaly / physiopathology
  • Mutation
  • Transcription Factors / genetics*

Substances

  • DNA-Binding Proteins
  • Transcription Factors
  • ASH1L protein, human
  • Histone-Lysine N-Methyltransferase