Primary congenital and developmental glaucomas

Hum Mol Genet. 2017 Aug 1;26(R1):R28-R36. doi: 10.1093/hmg/ddx205.

Abstract

Glaucoma is the leading cause of irreversible blindness worldwide. Although most glaucoma patients are elderly, congenital glaucoma and glaucomas of childhood are also important causes of visual disability. Primary congenital glaucoma (PCG) is isolated, non-syndromic glaucoma that occurs in the first three years of life and is a major cause of childhood blindness. Other early-onset glaucomas may arise secondary to developmental abnormalities, such as glaucomas that occur with aniridia or as part of Axenfeld-Rieger syndrome. Congenital and childhood glaucomas have strong genetic bases and disease-causing mutations have been discovered in several genes. Mutations in three genes (CYP1B1, LTBP2, TEK) have been reported in PCG patients. Axenfeld-Rieger syndrome is caused by mutations in PITX2 or FOXC1 and aniridia is caused by PAX6 mutations. This review discusses the roles of these genes in primary congenital glaucoma and glaucomas of childhood.

Publication types

  • Review

MeSH terms

  • Aniridia / genetics
  • Anterior Eye Segment / abnormalities
  • Anterior Eye Segment / metabolism
  • Cytochrome P-450 CYP1B1 / genetics
  • Cytochrome P-450 CYP1B1 / metabolism
  • Eye Abnormalities / genetics
  • Eye Abnormalities / metabolism
  • Eye Diseases, Hereditary
  • Eye Proteins / genetics
  • Forkhead Transcription Factors / genetics
  • Forkhead Transcription Factors / metabolism
  • Glaucoma / congenital*
  • Glaucoma / genetics*
  • Homeobox Protein PITX2
  • Homeodomain Proteins / genetics
  • Homeodomain Proteins / metabolism
  • Humans
  • Latent TGF-beta Binding Proteins / genetics
  • Latent TGF-beta Binding Proteins / metabolism
  • Mutation
  • PAX6 Transcription Factor / genetics
  • PAX6 Transcription Factor / metabolism
  • Transcription Factors / genetics
  • Transcription Factors / metabolism

Substances

  • Eye Proteins
  • FOXC1 protein, human
  • Forkhead Transcription Factors
  • Homeodomain Proteins
  • LTBP2 protein, human
  • Latent TGF-beta Binding Proteins
  • PAX6 Transcription Factor
  • PAX6 protein, human
  • Transcription Factors
  • CYP1B1 protein, human
  • Cytochrome P-450 CYP1B1

Supplementary concepts

  • Axenfeld-Rieger syndrome