Suppression of the ATP-binding cassette transporter ABCC4 impairs neuroblastoma tumour growth and sensitises to irinotecan in vivo

Eur J Cancer. 2017 Sep:83:132-141. doi: 10.1016/j.ejca.2017.06.024. Epub 2017 Jul 20.

Abstract

The ATP-binding cassette transporter ABCC4 (multidrug resistance protein 4, MRP4) mRNA level is a strong predictor of poor clinical outcome in neuroblastoma which may relate to its export of endogenous signalling molecules and chemotherapeutic agents. We sought to determine whether ABCC4 contributes to development, growth and drug response in neuroblastoma in vivo. In neuroblastoma patients, high ABCC4 protein levels were associated with reduced overall survival. Inducible knockdown of ABCC4 strongly inhibited the growth of human neuroblastoma cells in vitro and impaired the growth of neuroblastoma xenografts. Loss of Abcc4 in the Th-MYCN transgenic neuroblastoma mouse model did not impact tumour formation; however, Abcc4-null neuroblastomas were strongly sensitised to the ABCC4 substrate drug irinotecan. Our findings demonstrate a role for ABCC4 in neuroblastoma cell proliferation and chemoresistance and provide rationale for a strategy where inhibition of ABCC4 should both attenuate the growth of neuroblastoma and sensitise tumours to ABCC4 chemotherapeutic substrates.

Keywords: ABCC4; Chemotherapy; Drug resistance; Neuroblastoma; Xenograft.

MeSH terms

  • Animals
  • Antineoplastic Agents, Phytogenic / pharmacology*
  • Blotting, Western
  • Camptothecin / analogs & derivatives*
  • Camptothecin / pharmacology
  • Cell Line, Tumor
  • Cell Proliferation / drug effects
  • Disease Models, Animal
  • Doxycycline / pharmacology
  • Heterografts / drug effects
  • Irinotecan
  • Mice
  • Mice, Knockout
  • Multidrug Resistance-Associated Proteins / deficiency*
  • Multidrug Resistance-Associated Proteins / physiology
  • Neuroblastoma / drug therapy*
  • Tumor Cells, Cultured
  • Xenograft Model Antitumor Assays

Substances

  • ABCC4 protein, human
  • Antineoplastic Agents, Phytogenic
  • Multidrug Resistance-Associated Proteins
  • Irinotecan
  • Doxycycline
  • Camptothecin