The N-Terminal Domain of ALS-Linked TDP-43 Assembles without Misfolding

Angew Chem Int Ed Engl. 2017 Oct 2;56(41):12590-12593. doi: 10.1002/anie.201706769. Epub 2017 Sep 5.

Abstract

Transactivation response element (TAR) DNA-binding protein 43 (TDP-43) misfolding is implicated in several neurodegenerative diseases characterized by aggregated protein inclusions. Misfolding is believed to be mediated by both the N- and C-terminus of TDP-43; however, the mechanistic basis of the contribution of individual domains in the process remained elusive. Here, using single-molecule fluorescence and ensemble biophysical techniques, and a wide range of pH and temperature conditions, we show that TDP-43NTD is thermodynamically stable, well-folded and undergoes reversible oligomerization. We propose that, in full-length TDP-43, association between folded N-terminal domains enhances the propensity of the intrinsically unfolded C-terminal domains to drive pathological aggregation.

Keywords: amyotrophic lateral sclerosis; misfolding; neurodegenerative diseases; protein phase diagram; smFRET.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Amyotrophic Lateral Sclerosis / pathology*
  • DNA-Binding Proteins / chemistry*
  • Humans
  • Hydrogen-Ion Concentration
  • Models, Molecular
  • Protein Aggregation, Pathological / pathology
  • Protein Domains
  • Protein Folding*
  • Protein Multimerization
  • Thermodynamics

Substances

  • DNA-Binding Proteins
  • TARDBP protein, human