Attenuated PDGF signaling drives alveolar and microvascular defects in neonatal chronic lung disease

EMBO Mol Med. 2017 Nov;9(11):1504-1520. doi: 10.15252/emmm.201607308.

Abstract

Neonatal chronic lung disease (nCLD) affects a significant number of neonates receiving mechanical ventilation with oxygen-rich gas (MV-O2). Regardless, the primary molecular driver of the disease remains elusive. We discover significant enrichment for SNPs in the PDGF-Rα gene in preterms with nCLD and directly test the effect of PDGF-Rα haploinsufficiency on the development of nCLD using a preclinical mouse model of MV-O2 In the context of MV-O2, attenuated PDGF signaling independently contributes to defective septation and endothelial cell apoptosis stemming from a PDGF-Rα-dependent reduction in lung VEGF-A. TGF-β contributes to the PDGF-Rα-dependent decrease in myofibroblast function. Remarkably, endotracheal treatment with exogenous PDGF-A rescues both the lung defects in haploinsufficient mice undergoing MV-O2 Overall, our results establish attenuated PDGF signaling as an important driver of nCLD pathology with provision of PDGF-A as a protective strategy for newborns undergoing MV-O2.

Keywords: PDGF‐Rα; VEGF‐A; bronchopulmonary dysplasia; neonatal chronic lung disease; transforming growth factor‐β.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Animals
  • Animals, Newborn
  • Cells, Cultured
  • Chronic Disease
  • Fibroblasts / cytology
  • Fibroblasts / metabolism
  • Haploinsufficiency
  • Human Umbilical Vein Endothelial Cells
  • Humans
  • Infant, Newborn
  • Lung / metabolism
  • Lung Diseases / metabolism
  • Lung Diseases / pathology*
  • Lung Diseases / prevention & control
  • Mice
  • Mice, Inbred C57BL
  • Oxygen / metabolism
  • Platelet-Derived Growth Factor / metabolism*
  • Platelet-Derived Growth Factor / pharmacology
  • Platelet-Derived Growth Factor / therapeutic use
  • Receptor, Platelet-Derived Growth Factor alpha / antagonists & inhibitors
  • Receptor, Platelet-Derived Growth Factor alpha / genetics
  • Receptor, Platelet-Derived Growth Factor alpha / metabolism
  • Respiration, Artificial
  • Signal Transduction / drug effects
  • Vascular Endothelial Growth Factor A / metabolism

Substances

  • Platelet-Derived Growth Factor
  • Vascular Endothelial Growth Factor A
  • platelet-derived growth factor A
  • Receptor, Platelet-Derived Growth Factor alpha
  • Oxygen