A comparison of TAFRO syndrome between Japanese and non-Japanese cases: a case report and literature review

Ann Hematol. 2018 Mar;97(3):401-407. doi: 10.1007/s00277-017-3138-z. Epub 2017 Sep 27.

Abstract

TAFRO syndrome was first described as a variant of multicentric Castleman's disease with thrombocytopenia, anasarca, fever, renal dysfunction, and organomegaly. We report the case of a 25-year-old Caucasian male with diagnosis of TAFRO syndrome and present a literature review. The objective of the study was to compare TAFRO syndrome between Japanese and non-Japanese patients. Cases were included by searching the term "TAFRO" in the Medline database using PubMed between 2010 and 2016. The Student t test and Mann-Whitney U test were used to compare continuous variables. Fisher's exact test was used for categorical variables. Statistical significance was set at p < 0.05. Forty-four cases were included. Thirty-two patients (73%) were of Japanese origin. Japanese patients were significantly older than non-Japanese ones (52.0 ± 13.6 years versus 36.9 ± 19.8 years, p = 0.0064) but there was no difference in gender. Creatinine level on admission was significantly higher in the non-Japanese group (1.87 ± 0.84 mg/dL versus 1.32 ± 0.57 mg/dL, p = 0.0347). There were no significant differences concerning lymphadenopathy, elevated number of megakaryocytes on bone marrow aspiration, autoimmune abnormalities, and the following parameters on admission: platelet count, hemoglobin, albumin, alkaline phosphatase (ALP). Corticotherapy was always used on induction for Japanese patients while it was only used in 75% of the cases on induction in non-Japanese patients (p = 0.0166). Our study was the first to compare TAFRO syndrome according to ethnicity. Japanese patients were significantly older and had a significantly lower creatinine level on admission than non-Japanese patients.

Keywords: Castleman; Ethnic differences; Japanese; TAFRO.

Publication types

  • Case Reports
  • Review

MeSH terms

  • Adult
  • Castleman Disease / complications
  • Castleman Disease / ethnology
  • Castleman Disease / pathology*
  • Edema / complications
  • Edema / ethnology
  • Edema / pathology*
  • Fever / complications
  • Fever / ethnology
  • Fever / pathology
  • Humans
  • Hypertrophy / complications
  • Hypertrophy / pathology
  • Japan
  • Kidney Diseases / complications
  • Kidney Diseases / ethnology
  • Kidney Diseases / pathology*
  • Male
  • Syndrome
  • Thrombocytopenia / complications
  • Thrombocytopenia / ethnology
  • Thrombocytopenia / pathology*

Supplementary concepts

  • Multi-centric Castleman's Disease