Pharmacokinetic Modelling to Predict FVIII:C Response to Desmopressin and Its Reproducibility in Nonsevere Haemophilia A Patients

Thromb Haemost. 2018 Apr;118(4):621-629. doi: 10.1160/TH17-06-0390. Epub 2018 Feb 19.

Abstract

Background: Nonsevere haemophilia A (HA) patients can be treated with desmopressin. Response of factor VIII activity (FVIII:C) differs between patients and is difficult to predict.

Objectives: Our aims were to describe FVIII:C response after desmopressin and its reproducibility by population pharmacokinetic (PK) modelling.

Patients and methods: Retrospective data of 128 nonsevere HA patients (age 7-75 years) receiving an intravenous or intranasal dose of desmopressin were used. PK modelling of FVIII:C was performed by nonlinear mixed effect modelling. Reproducibility of FVIII:C response was defined as less than 25% difference in peak FVIII:C between administrations.

Results: A total of 623 FVIII:C measurements from 142 desmopressin administrations were available; 14 patients had received two administrations at different occasions. The FVIII:C time profile was best described by a two-compartment model with first-order absorption and elimination. Interindividual variability of the estimated baseline FVIII:C, central volume of distribution and clearance were 37, 43 and 50%, respectively. The most recently measured FVIII:C (FVIII-recent) was significantly associated with FVIII:C response to desmopressin (p < 0.001). Desmopressin administration resulted in an absolute FVIII:C increase of 0.47 IU/mL (median, interquartile range: 0.32-0.65 IU/mL, n = 142).

Fviii: C response was reproducible in 6 out of 14 patients receiving two desmopressin administrations.

Conclusion: FVIII:C response to desmopressin in nonsevere HA patients was adequately described by a population PK model. Large variability in FVIII:C response was observed, which could only partially be explained by FVIII-recent.

Fviii: C response was not reproducible in a small subset of patients. Therefore, monitoring FVIII:C around surgeries or bleeding might be considered. Research is needed to study this further.

MeSH terms

  • Adolescent
  • Adult
  • Aged
  • Blood Coagulation Tests
  • Child
  • Deamino Arginine Vasopressin / pharmacokinetics*
  • Factor VIII / pharmacokinetics*
  • Hemophilia A / drug therapy*
  • Hemorrhage / drug therapy*
  • Humans
  • Middle Aged
  • Mutation
  • Nonlinear Dynamics
  • Reproducibility of Results
  • Retrospective Studies
  • Young Adult

Substances

  • Factor VIII
  • Deamino Arginine Vasopressin