Amusia and its electrophysiological correlates in neurofibromatosis type 1

Arq Neuropsiquiatr. 2018 May;76(5):287-295. doi: 10.1590/0004-282X20180031.

Abstract

Introduction: Auditory processing deficits are common in people with neurofibromatosis type 1 (NF1) and they often report difficulties in musical performance.

Objective: We investigated whether NF1 could be associated with amusia as well as with some impairment of primary auditory cortex activity.

Methods: Eighteen people with NF1 and 22 healthy volunteers, matched for age, sex and educational level, were evaluated with the Montreal Battery Evaluation of Amusia - short version. The integrity of cortical primary auditory processing areas was evaluated by evoked potential mismatch negativity.

Results: Amusia was correlated with NF1 (p = 0.001, odds ratio = 42.0, confidence interval 4.5-39.6). Patients with NF1 exhibited a greater prevalence of amusia than healthy controls (67% vs. 4.5%) and difficulties in both melodic and temporal music perception. Worse performance on the Montreal Battery Evaluation of Amusia was correlated with a greater mismatch negativity latency in NF1 group.

Conclusions: Amusia is a common feature in NF1 and may result from impairment of activity in primary auditory processing areas.

Publication types

  • Observational Study

MeSH terms

  • Adolescent
  • Adult
  • Auditory Perceptual Disorders / diagnosis
  • Auditory Perceptual Disorders / etiology*
  • Auditory Perceptual Disorders / physiopathology
  • Case-Control Studies
  • Cross-Sectional Studies
  • Electrophysiological Phenomena
  • Evoked Potentials, Auditory / physiology*
  • Female
  • Humans
  • Male
  • Music*
  • Neurofibromatosis 1 / complications*
  • Neurofibromatosis 1 / physiopathology
  • Neuropsychological Tests
  • Young Adult