Recurrent hepatic failure and status epilepticus: an uncommon presentation of hyperargininemia

Metab Brain Dis. 2018 Oct;33(5):1775-1778. doi: 10.1007/s11011-018-0281-8. Epub 2018 Jun 30.

Abstract

Argininemia is a rare hereditary disease due to a deficiency of hepatic arginase, which is the last enzyme of the urea cycle and hydrolyzes arginine to ornithine and urea. Herein we report a patient with arginase I (ARG1) deficiency who presented with recurrent nonconvulsive status epilepticus and liver failure. A novel homozygous frameshift mutation c.703_707delGGACTinsAGACTGGACC (p.G235Rfs*20) was detected.

Keywords: Children; Hyperargininemia; Recurrent hepatic failure; Status epilepticus.

Publication types

  • Case Reports

MeSH terms

  • Arginase / genetics*
  • Brain / diagnostic imaging
  • Child, Preschool
  • Female
  • Humans
  • Hyperargininemia / complications*
  • Hyperargininemia / diagnostic imaging
  • Hyperargininemia / genetics
  • Liver Failure / diagnostic imaging
  • Liver Failure / etiology*
  • Liver Failure / genetics
  • Magnetic Resonance Imaging
  • Status Epilepticus / diagnostic imaging
  • Status Epilepticus / etiology*
  • Status Epilepticus / genetics

Substances

  • ARG1 protein, human
  • Arginase