Recurrent Rathke's Cleft Cysts: Incidence and Surgical Management in a Tertiary Pituitary Center over 2 Decades

Oper Neurosurg (Hagerstown). 2019 Jun 1;16(6):675-684. doi: 10.1093/ons/opy258.

Abstract

Background: Limited data exist pertaining to outcomes following surgery for recurrent Rathke's cleft cysts (RCC).

Objective: To determine treatment outcomes in patients undergoing reoperation for recurrent or residual RCCs.

Methods: A retrospective analysis of 112 consecutive RCC operations in 109 patients between 1995 and 2017 was conducted.

Results: Eighteen patients underwent 21 RCC reoperations with a mean follow-up of 58 mo. Patient symptoms prior to reoperation included headaches (14, 66.7%) and vision loss (12, 57.1%). Thirteen of 18 patients (72.2%) required hormone supplementation prior to reoperation including 5 with diabetes insipidus (DI). Mean RCC diameter was 16 mm and 76% had suprasellar extension. Compared to index RCC cases, intraoperative cerebrospinal fluid leak repair was more common in reoperation cases (15/21, 71% vs 43/91, 47%, P = .05). There was 1 carotid artery injury without neurological sequelae, and 2 postoperative cerebrospinal fluid (CSF) leaks (9.5%). Rates of transient hyponatremia (3/10, 30% vs 4/91, 4.4%, P = .04) and transient DI (5/10, 50% vs 17/91, 18.7%, P = .04) were higher in the reoperation vs index group. Improved headaches and vision were reported in 4/12 (33%) and 8/12 (61.5%) of RCC reoperation patients, respectively. Two patients developed new permanent DI. A higher proportion of reoperation patients had RCC squamous metaplasia (24% vs 5.4%, P = .02) or wall inflammation (42.9% vs 2.2%, P < .001) on pathological examination.

Conclusion: Reoperation for RCCs is generally safe at tertiary pituitary centers and often results in improved vision. Hypopituitarism is less likely to improve following reoperation for recurrent RCCs. Several histopathological features may help characterize "atypical RCCs" with a higher likelihood of recurrence/progression.

Keywords: Complications; Endoscopic endonasal approach; Microsurgery; Rathke's cleft cyst; Recurrence; Transsphenoidal.

MeSH terms

  • Adrenocorticotropic Hormone / deficiency
  • Adult
  • Aged
  • Carotid Artery Injuries / epidemiology
  • Central Nervous System Cysts / complications
  • Central Nervous System Cysts / surgery*
  • Cerebrospinal Fluid Leak / epidemiology
  • Cerebrospinal Fluid Leak / surgery
  • Craniotomy
  • Diabetes Insipidus / drug therapy
  • Diabetes Insipidus / epidemiology
  • Diabetes Insipidus / etiology
  • Female
  • Glucocorticoids / therapeutic use
  • Humans
  • Hypogonadism / drug therapy
  • Hypogonadism / etiology
  • Hypothyroidism / drug therapy
  • Hypothyroidism / etiology
  • Inappropriate ADH Syndrome / drug therapy
  • Inappropriate ADH Syndrome / epidemiology
  • Incidence
  • Intraoperative Complications / surgery
  • Male
  • Microsurgery
  • Middle Aged
  • Neoplasm Recurrence, Local / epidemiology
  • Neoplasm Recurrence, Local / surgery*
  • Neuroendoscopy
  • Pituitary Neoplasms / complications
  • Pituitary Neoplasms / surgery*
  • Postoperative Complications / epidemiology
  • Reoperation
  • Tertiary Care Centers

Substances

  • Glucocorticoids
  • Adrenocorticotropic Hormone