Skin α-synuclein deposits differ in clinical variants of synucleinopathy: an in vivo study

Sci Rep. 2018 Sep 24;8(1):14246. doi: 10.1038/s41598-018-32588-8.

Abstract

We aimed to characterize in vivo α-synuclein (α-syn) aggregates in skin nerves to ascertain: 1) the optimal marker to identify them; 2) possible differences between synucleinopathies that may justify the clinical variability. We studied multiple skin nerve α-syn deposits in 44 patients with synucleinopathy: 15 idiopathic Parkinson's disease (IPD), 12 dementia with Lewy Bodies (DLB), 5 pure autonomic failure (PAF) and 12 multiple system atrophy (MSA). Ten healthy subjects were used as controls. Antibodies against native α-syn, C-terminal α-syn epitopes such as phosphorylation at serine 129 (p-syn) and to conformation-specific for α-syn mature amyloid fibrils (syn-F1) were used. We found that p-syn showed the highest sensitivity and specificity in disclosing skin α-syn deposits. In MSA abnormal deposits were only found in somatic fibers mainly at distal sites differently from PAF, IPD and DLB displaying α-syn deposits in autonomic fibers mainly at proximal sites. PAF and DLB showed the highest p-syn load with a widespread involvement of autonomic skin nerve fibers.

In conclusion: 1) p-syn in skin nerves was the optimal marker for the in vivo diagnosis of synucleinopathies; 2) the localization and load differences of aggregates may help to identify specific diagnostic traits and support a different pathogenesis among synucleinopathies.

MeSH terms

  • Aged
  • Aged, 80 and over
  • Amyloid / genetics
  • Amyloid / metabolism
  • Brain / metabolism
  • Brain / pathology
  • Female
  • Humans
  • Lewy Body Disease / genetics
  • Lewy Body Disease / metabolism
  • Lewy Body Disease / pathology
  • Male
  • Multiple System Atrophy / genetics
  • Multiple System Atrophy / metabolism
  • Multiple System Atrophy / pathology
  • Nerve Fibers / metabolism
  • Nerve Fibers / pathology
  • Parkinson Disease / genetics
  • Parkinson Disease / metabolism
  • Parkinson Disease / pathology
  • Protein Aggregation, Pathological / genetics*
  • Pure Autonomic Failure / genetics
  • Pure Autonomic Failure / metabolism
  • Pure Autonomic Failure / pathology
  • Skin / innervation
  • Skin / metabolism*
  • Skin / pathology
  • Skin Diseases / diagnosis
  • Skin Diseases / genetics*
  • Skin Diseases / metabolism
  • Skin Diseases / pathology
  • alpha-Synuclein / genetics*

Substances

  • Amyloid
  • alpha-Synuclein