Clinical approach to cardiac pauses in congenital central hypoventilation syndrome

Pediatr Pulmonol. 2019 Feb;54(2):E4-E6. doi: 10.1002/ppul.24189. Epub 2018 Nov 20.

Abstract

Congenital central hypoventilation syndrome (CCHS) patients may have heart rhythm disorders related to autonomic nervous system dysfunction such as, sinus bradycardia and transient asystole with potentially dramatic syncopal events. The diagnosis of these cardiac alterations may be challenging with conventional periodical Holter monitoring. The case shows how continuous heart rhythm monitoring provided by the implantable cardiac monitor (ICM) may play a crucial role for their early diagnosis and the choice of the appropriate therapeutic intervention.

Keywords: cardiac pauses; congenital central hypoventilation syndrome; diaphragm pacing system; implantable cardiac monitor; implantable cardiac pacemaker.

Publication types

  • Case Reports

MeSH terms

  • Adolescent
  • Electrocardiography
  • Female
  • Heart / physiopathology
  • Humans
  • Hypoventilation / congenital*
  • Hypoventilation / diagnosis
  • Hypoventilation / physiopathology
  • Hypoventilation / therapy
  • Pacemaker, Artificial
  • Sleep Apnea, Central* / diagnosis
  • Sleep Apnea, Central* / physiopathology
  • Sleep Apnea, Central* / therapy

Supplementary concepts

  • Congenital central hypoventilation syndrome