A three-year-old boy with hypodipsic hypernatremia syndrome

Pan Afr Med J. 2018 Aug 6:30:250. doi: 10.11604/pamj.2018.30.250.12263. eCollection 2018.

Abstract

We describe a three-year-old boy who had a growth and psychomotor retardation associated with inappropriate lack of thirst and vasopressin secretion in the presence of chronic plasma hyperosmolarity. Computed brain tomography revealed bilateral supratentorial sub-ependymal and cortical calcifications. Dissociation in the plasma vasopressin response to osmotic change was demonstrated in this patient. Treatment with a vasopressin analogue, desamino-D-arginine vasopressin (DDAVP) and forced intake of water restored plasma osmolality and serum sodium levels to normal.

Keywords: Brain calcifications; child; hypodipsic hypernatremia syndrome.

Publication types

  • Case Reports

MeSH terms

  • Antidiuretic Agents / administration & dosage
  • Brain / diagnostic imaging
  • Child, Preschool
  • Deamino Arginine Vasopressin / administration & dosage*
  • Humans
  • Hypernatremia / diagnosis*
  • Hypernatremia / therapy
  • Male
  • Osmolar Concentration*
  • Sodium / blood
  • Syndrome
  • Thirst*
  • Tomography, X-Ray Computed / methods

Substances

  • Antidiuretic Agents
  • Sodium
  • Deamino Arginine Vasopressin