Presentation of pseudohypoparathyroidism and pseudopseudohypoparathyroidism with skin lesions: Case reports and review

Pediatr Dermatol. 2019 May;36(3):355-359. doi: 10.1111/pde.13769. Epub 2019 Feb 27.

Abstract

We report three cases of patients with pseudohypoparathyroidism or pseudopseudohypoparathyroidism. These diseases are considered GNAS inactivating mutation syndromes that are characterized by a diversity of alterations among which a particular phenotype and specific endocrine or ossification abnormalities may be found. These patients may present with hard cutaneous nodules, which can represent osteoma cutis. The presence of these lesions in pediatric patients should prompt the dermatologist's consideration of this group of diseases when reaching a diagnosis. A multidisciplinary team of pediatricians, endocrinologists, geneticists, and dermatologists should carefully evaluate these patients.

Keywords: GNAS; imprinting; inactivating mutation; pediatrics; pseudohypoparathyroidism; pseudopseudohypoparathyroidism.

Publication types

  • Case Reports
  • Review

MeSH terms

  • Adolescent
  • Child
  • Female
  • Humans
  • Male
  • Pseudohypoparathyroidism / complications*
  • Pseudohypoparathyroidism / diagnosis*
  • Pseudopseudohypoparathyroidism / complications*
  • Pseudopseudohypoparathyroidism / diagnosis*
  • Skin Diseases / diagnostic imaging
  • Skin Diseases / etiology*
  • Skin Diseases / pathology