Secreted cellular prion protein binds doxorubicin and correlates with anthracycline resistance in breast cancer

JCI Insight. 2019 Feb 26;5(6):e124092. doi: 10.1172/jci.insight.124092.

Abstract

Anthracyclines are amongst the most effective chemotherapeutics ever developed, but they produce grueling side-effects, serious adverse events and resistance often develops over time. We found that these compounds can be sequestered by secreted cellular Prion protein (PrPC), blocking their cytotoxic activity. This effect was dose-dependent using either cell line-conditioned medium or human serum as a source of PrPC. Genetic depletion of PrPC or inhibition of binding via chelation of ionic copper prevented the interaction and restored cytotoxic activity. This was more pronounced for doxorubicin than its epimer, epirubicin. Investigating the relevance to breast cancer management, we found that the levels of PRNP transcript in pre-treatment tumor biopsies stratified relapse-free survival after neoadjuvant treatment with anthracyclines, particularly amongst doxorubicin-treated patients with residual disease at surgery (p=2.8E-08). These data suggest that local sequestration could mediate treatment resistance. Consistent with this, tumor cell expression of PrPC protein correlated with poorer response to doxorubicin but not epirubicin in an independent cohort analyzed by immunohistochemistry, particularly soluble isoforms released into the extracellular environment by shedding (p=0.015). These findings have important potential clinical implications for frontline regimen decision-making. We suggest there is warranted utility for prognostic PrPC/PRNP assays to guide chemo-sensitization strategies that exploit an understanding of PrPC-anthracycline-copper ion complexes.

Keywords: Cell Biology; Oncology; Prions.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Adult
  • Anthracyclines / pharmacology*
  • Anthracyclines / therapeutic use
  • Antibiotics, Antineoplastic / pharmacology*
  • Antibiotics, Antineoplastic / therapeutic use
  • Biomarkers, Tumor / blood
  • Biomarkers, Tumor / genetics
  • Biomarkers, Tumor / metabolism*
  • Breast Neoplasms / blood
  • Breast Neoplasms / drug therapy*
  • Breast Neoplasms / genetics
  • Breast Neoplasms / mortality
  • Cell Line, Tumor
  • Culture Media, Conditioned / metabolism
  • Datasets as Topic
  • Disease-Free Survival
  • Doxorubicin / pharmacology
  • Doxorubicin / therapeutic use
  • Drug Resistance, Neoplasm / genetics*
  • Epirubicin / pharmacology
  • Epirubicin / therapeutic use
  • Female
  • Follow-Up Studies
  • Gene Expression Regulation, Neoplastic
  • Gene Knockdown Techniques
  • Humans
  • Kaplan-Meier Estimate
  • Middle Aged
  • Patient Selection
  • Prion Proteins / blood
  • Prion Proteins / genetics
  • Prion Proteins / metabolism*
  • Prognosis
  • Protein Binding
  • Protein Isoforms / blood
  • Protein Isoforms / genetics
  • Protein Isoforms / metabolism
  • RNA, Small Interfering / metabolism

Substances

  • Anthracyclines
  • Antibiotics, Antineoplastic
  • Biomarkers, Tumor
  • Culture Media, Conditioned
  • PRNP protein, human
  • Prion Proteins
  • Protein Isoforms
  • RNA, Small Interfering
  • Epirubicin
  • Doxorubicin