Purpose: To describe a case of bilateral choroidal osteoma (CO) in a patient with a history of langerhans cell histiocytosis (LCH).
Methods: A 24-year-old man complaining of gradually decreasing visual acuity in both eyes is presented. He had a history of lymphadenopathy, respiratory symptoms, and pathology-proven diagnosis of LCH.
Results: Ophthalmic clinical and imaging studies revealed bilateral CO.
Conclusion: In this patient, we suggest a possible relationship between LCH and CO.
Keywords: Bilateral; Choroidal osteoma; Langerhans cell histiocytosis.