Etiology, presenting features and outcome of children with non-cirrhotic portal vein thrombosis: A multicentre national study

Dig Liver Dis. 2019 Aug;51(8):1179-1184. doi: 10.1016/j.dld.2019.02.014. Epub 2019 Mar 6.

Abstract

Objectives: Non-cirrhotic portal vein thrombosis (PVT) is a main cause of portal hypertension in children. We describe the characteristics at presentation and outcome of a cohort of patients with PVT to determine clinical features and predictors of outcome.

Methods: We recorded: (1) Associated factors: prematurity, congenital malformations, neonatal illnesses, umbilical vein catheterization (UVC), deep infections, surgery; (2) congenital and acquired prothrombotic disorders; (3) features at last follow up including survival rate and need for surgery.

Results: 187 patients, mean age at diagnosis 4 ± 3.7 years, had a history of prematurity (61%); UVC (65%); neonatal illnesses (79%). The diagnosis followed the detection of splenomegaly (40%), gastrointestinal bleeding (36%), hypersplenism (6%), or was incidental (18%). Of 71 patients who had endoscopy at presentation 62 (87%) had oesophageal varices. After 11.3 years' follow up 63 (34%) required surgery or TIPS. Ten-year survival rate was 98%, with 90% shunt patency. Spleen size, variceal bleeding and hypersplenism at presentation were predictors of surgery or TIPS (p < 0.05).

Conclusion: PVT is associated with congenital and acquired co-morbidities. History of prematurity, neonatal illnesses and UVC should lead to rule out PVT. Large spleen, variceal bleeding and hypersplenism at presentation predict the need for eventual surgery in a third of cases.

Keywords: Children; Extra-hepatic portal vein obstruction; Non-cirrhotic portal hypertension; Portal vein thrombosis.

Publication types

  • Multicenter Study

MeSH terms

  • Adolescent
  • Catheterization / adverse effects
  • Child
  • Child, Preschool
  • Esophageal and Gastric Varices / complications*
  • Esophageal and Gastric Varices / etiology
  • Female
  • Gastrointestinal Hemorrhage / etiology
  • Gastrointestinal Hemorrhage / mortality
  • Gastrointestinal Hemorrhage / surgery*
  • Humans
  • Hypersplenism / epidemiology
  • Hypertension, Portal / etiology
  • Infant
  • Infant, Newborn
  • Infant, Newborn, Diseases / epidemiology
  • Infant, Premature
  • Italy / epidemiology
  • Male
  • Portal Vein / physiopathology*
  • Portasystemic Shunt, Transjugular Intrahepatic / adverse effects
  • Splenomegaly / etiology
  • Venous Thrombosis / etiology*
  • Venous Thrombosis / mortality
  • Venous Thrombosis / surgery*