Improving the quality of care in the molecular era for children and adolescents with medulloblastoma

Clin Transl Oncol. 2019 Dec;21(12):1687-1698. doi: 10.1007/s12094-019-02101-2. Epub 2019 Apr 1.

Abstract

Purpose: Elevated mortality and morbidity rates persist in pediatric patients with medulloblastoma. We present a clinical audit of a real-world cohort of patients in search for pragmatic measures to improve their management and outcome.

Methods/patients: All pediatric patients with medulloblastoma treated between 2003 and 2016 at a Spanish reference center were reviewed. In the absence of internationally accepted quality indicators (QIs) for pediatric CNS tumors, diagnostic, therapeutic, survival, and time QIs were defined and assessed.

Results: Fifty-eight patients were included, 24% were younger children (< 3 years), 36% high risk (anaplastic, metastasis, or surgical residue > 1.5 cm2), and 40% standard risk. Five-year OS was 59.2% (95% CI 47-75); 5-year PFS 36.4% (95% CI 25-53). Five main areas of quality assurance were identified: diagnosis, global strategy, frontline treatment modalities, outcomes, and long-term and end-of-life care. A set of 34 QIs was developed and applied. Lack of central pathology review, delay in the incorporation of novel molecular markers, and absence of a neurocognitive and quality-of-life evaluation program were some of the audit findings.

Conclusions: This real-world research study resulted in the development of a pragmatic set of QIs, aimed to improve clinical audits and quality of care given to children and adolescents with medulloblastoma. We hope that our findings will serve as a reference to further develop a quality assurance system with specific QIs for pediatric CNS tumors in the future and that this will ultimately improve the survival and quality of life of these patients.

Keywords: CNS tumors; Childhood; Medulloblastoma; Quality assurance; Quality of care; Real-world studies.

MeSH terms

  • Adolescent
  • Cerebellar Neoplasms / therapy*
  • Child
  • Child, Preschool
  • Female
  • Hospitals, Pediatric / statistics & numerical data
  • Humans
  • Infant
  • Male
  • Medulloblastoma / therapy*
  • Neoplasm Recurrence, Local
  • Prognosis
  • Progression-Free Survival
  • Quality Assurance, Health Care
  • Quality of Health Care*
  • Spain
  • Treatment Outcome