Retrospective Study of Patients with Hyperphenylalaninemia- Experience from a Tertiary Care Center in Pakistan

J Pak Med Assoc. 2019 Apr;69(4):509-513.

Abstract

Objective: To assess the clinical and biochemical features as well as outcome of hyperphenylalaninemia patients.

Methods: The descriptive retrospective study was conducted at the Aga Khan University Hospital, Karachi, and comprised data from January 2013 to February 2017 of plasma amino acid analysed at the Biochemical Genetic Laboratory of patients with phenylalanine levels >120 umol/L. Medical charts of patients registered with the Metabolic Clinics were reviewed, while outside referrals were contacted by telephone to collect data on a pre-structured questionnaire. Data was analysed using SPSS 21.

Results: Of the 18 patients, 13(72%) were males. Overall median age was 606 days (interquartile range: 761) and median phenylalanine levels were 1280 (interquartile range: 935) umol/L. Phenylalanine hydroxylase deficiency was present in 5(28%) patients while 3(16.6%) had defects in the metabolism or regeneration of tetrahydrobiopterin. The most common clinical features was intellectual deficit and seizures 14(78%) each, followed by lighter hair colour 10(55.5%) and hypotonia 11(61%). High treatment cost was the leading reason for cessation of therapy in 7(39%) followed by refusal by patient's family 5(28%).

Conclusions: Most hyperphenylalaninemia cases were diagnosed late when intellectual disability had already developed.

Keywords: Phenylalanine, Hyperphenylalaninemia, Classification, Phenylalanine hydroxylase deficiency, Tetrahydrobiopterin defects..

MeSH terms

  • Anticonvulsants / therapeutic use
  • Biopterins / analogs & derivatives
  • Biopterins / metabolism
  • Child, Preschool
  • Cost of Illness
  • Delayed Diagnosis
  • Diet Therapy
  • Female
  • Humans
  • Infant
  • Intellectual Disability / etiology
  • Intellectual Disability / physiopathology*
  • Male
  • Muscle Hypotonia / etiology
  • Muscle Hypotonia / physiopathology*
  • Muscle Relaxants, Central / therapeutic use
  • Pakistan
  • Patient Acceptance of Health Care
  • Phenylalanine Hydroxylase / deficiency
  • Phenylketonurias / complications
  • Phenylketonurias / metabolism
  • Phenylketonurias / physiopathology*
  • Phenylketonurias / therapy
  • Retrospective Studies
  • Seizures / drug therapy
  • Seizures / etiology
  • Seizures / physiopathology*
  • Tertiary Care Centers
  • Treatment Refusal
  • Withholding Treatment

Substances

  • Anticonvulsants
  • Muscle Relaxants, Central
  • Biopterins
  • Phenylalanine Hydroxylase
  • sapropterin