Treatment and outcome of Unicentric Castleman Disease: a retrospective analysis of 71 cases

Br J Haematol. 2019 Jul;186(2):269-273. doi: 10.1111/bjh.15921. Epub 2019 Apr 23.

Abstract

We retrospectively analysed 71 cases of Unicentric Castleman disease, a rare, usually asymptomatic, benign lymphoproliferative disorder presenting as a unique nodal mass. Although surgery is considered as the gold standard therapy, only 38 patients (54%) underwent initial surgical resection and 95% were cured. An additional 9 patients had surgery after an attempt at medical reduction. Reduction therapy was used in 21 patients with a 55% response rate, but without evidence for an optimal regimen. Radiotherapy was limited to 8 patients because of associated toxicity. Watch and wait was considered in 13 asymptomatic patients and 11 of these remained stable for up to 17 years.

Keywords: Castleman disease; radiotherapy; surgery; watch-and-wait.

MeSH terms

  • Adult
  • Castleman Disease / mortality*
  • Castleman Disease / pathology*
  • Castleman Disease / therapy*
  • Disease-Free Survival
  • Female
  • Humans
  • Male
  • Middle Aged
  • Retrospective Studies
  • Survival Rate