Probabilistic modeling of personalized drug combinations from integrated chemical screen and molecular data in sarcoma

BMC Cancer. 2019 Jun 17;19(1):593. doi: 10.1186/s12885-019-5681-6.

Abstract

Background: Cancer patients with advanced disease routinely exhaust available clinical regimens and lack actionable genomic medicine results, leaving a large patient population without effective treatments options when their disease inevitably progresses. To address the unmet clinical need for evidence-based therapy assignment when standard clinical approaches have failed, we have developed a probabilistic computational modeling approach which integrates molecular sequencing data with functional assay data to develop patient-specific combination cancer treatments.

Methods: Tissue taken from a murine model of alveolar rhabdomyosarcoma was used to perform single agent drug screening and DNA/RNA sequencing experiments; results integrated via our computational modeling approach identified a synergistic personalized two-drug combination. Cells derived from the primary murine tumor were allografted into mouse models and used to validate the personalized two-drug combination. Computational modeling of single agent drug screening and RNA sequencing of multiple heterogenous sites from a single patient's epithelioid sarcoma identified a personalized two-drug combination effective across all tumor regions. The heterogeneity-consensus combination was validated in a xenograft model derived from the patient's primary tumor. Cell cultures derived from human and canine undifferentiated pleomorphic sarcoma were assayed by drug screen; computational modeling identified a resistance-abrogating two-drug combination common to both cell cultures. This combination was validated in vitro via a cell regrowth assay.

Results: Our computational modeling approach addresses three major challenges in personalized cancer therapy: synergistic drug combination predictions (validated in vitro and in vivo in a genetically engineered murine cancer model), identification of unifying therapeutic targets to overcome intra-tumor heterogeneity (validated in vivo in a human cancer xenograft), and mitigation of cancer cell resistance and rewiring mechanisms (validated in vitro in a human and canine cancer model).

Conclusions: These proof-of-concept studies support the use of an integrative functional approach to personalized combination therapy prediction for the population of high-risk cancer patients lacking viable clinical options and without actionable DNA sequencing-based therapy.

Keywords: Artificial intelligence and machine learning; Combination therapy; Computational modeling; Drug screening; High-throughput sequencing; Pediatric cancer; Personalized therapy; Sarcoma.

MeSH terms

  • Animals
  • Cell Line, Tumor
  • Computational Biology / methods*
  • Disease Models, Animal
  • Dogs
  • Drug Evaluation, Preclinical / methods*
  • Drug Synergism
  • Drug Therapy, Combination / methods*
  • Female
  • Heterografts
  • Humans
  • Kaplan-Meier Estimate
  • Mice
  • Mice, Inbred NOD
  • Models, Statistical*
  • Precision Medicine / methods*
  • Rhabdomyosarcoma, Alveolar / drug therapy*