Novel PLVAP Mutation in Protein Losing Enteropathy

Fetal Pediatr Pathol. 2019 Dec;38(6):534-537. doi: 10.1080/15513815.2019.1627624. Epub 2019 Jun 19.

Abstract

Introduction: A genetic cause of the protein-losing enteropathy (PLE) disease Diarrhea 10 (DIAR10) are mutations in the recently described PLVAP (plasmalemma vesicle protein). Case report: An infant with fatal PLE had a novel homozygous frameshift mutation (c.339dupT; p.Ala114Cysfs*9) leading to a premature stop codon in exon 1 of the PLVAP (NM_031310) gene detected by Whole Exome Sequencing (WES). Conclusion: The frameshift mutation (PLVAP; c.339dupT; p.Ala114Cysfs*9) we have described in our patient has not been previously reported. This is the fifth case reported with a mutation in PLVAP associated with PLE and DIAR10.

Keywords: Novel mutation; PLE; PLVAP.

Publication types

  • Case Reports

MeSH terms

  • Carrier Proteins / genetics*
  • Exons / genetics*
  • Female
  • Frameshift Mutation / genetics*
  • Homozygote
  • Humans
  • Infant
  • Mutation / genetics
  • Pedigree
  • Protein-Losing Enteropathies / diagnosis
  • Protein-Losing Enteropathies / genetics*

Substances

  • Carrier Proteins