Immune system defects in DiGeorge syndrome and association with clinical course

Scand J Immunol. 2019 Nov;90(5):e12809. doi: 10.1111/sji.12809. Epub 2019 Sep 9.

Abstract

We evaluated 18 DiGeorge syndrome (DGS) patients and aimed to investigate the immunological changes in this population. DGS patients with low naive CD4+ T and CD8+ T cells were defined as high-risk (HR) patients, whereas patients with normal numbers of naive CD4+ and CD8+ T cells were defined as standard risk (SR) patients. Level of serum IgM, CD3+ T cell counts and percentages of class-switched memory B cells were significantly low in HR group compared to SR ones. Severe infections and persistent hypoparathyroidism were detected significantly higher in HR group. Patients with reduced percentages of class-switched B cells had earlier onset of infection, lower blood IgM, lower CD4+ and CD8+ T counts than patients with normal class-switched memory B cells. Decreased levels of IgM were associated with low numbers of naive CD4+ and recent thymic emigrants T cells. Monitoring the immune changes of patients with DGS would be useful to predict the severe phenotype of disease.

Keywords: B cells; DiGeorge syndrome; T cells; antibodies/immunoglobulins; immunodeficiency.

MeSH terms

  • Adolescent
  • Adult
  • B-Lymphocytes / immunology*
  • CD4-Positive T-Lymphocytes / immunology*
  • CD8-Positive T-Lymphocytes / immunology*
  • Child
  • Child, Preschool
  • DiGeorge Syndrome / genetics
  • DiGeorge Syndrome / immunology*
  • Female
  • Humans
  • Hypoparathyroidism / diagnosis
  • Immunoglobulin Class Switching / immunology
  • Immunoglobulin M / blood*
  • Immunologic Memory / immunology
  • Infant
  • Lymphocyte Count
  • Male

Substances

  • Immunoglobulin M