[Analysis of SCN4A gene variation in a Chinese pedigree affected with skeletal muscle sodium channelopathies]

Zhonghua Yi Xue Yi Chuan Xue Za Zhi. 2019 Aug 10;36(8):809-812. doi: 10.3760/cma.j.issn.1003-9406.2019.08.014.
[Article in Chinese]

Abstract

Objective: To explore the clinical features of a Chinese pedigree affected with skeletal muscle sodium channelopathies due to variation of SCN4A gene.

Methods: Potential variation of the 24 exons of the SCN4A gene was screened using PCR and Sanger sequencing.

Results: Four family members were affected with the disease in an autosomal dominant inheritance pattern. Three patients had normekalemic periodic paralysis, while 1 showed paramyotonia congenita. Genetic analysis detected a missense variation c.2078T>C (p.Ile693Thr) in exon 13 of the SCN4A gene in the proband and other 3 affected relatives.

Conclusion: Normokalemic periodic paralysis and paramyotonia congenita can occur in different family members with skeletal muscle sodium channelopathies due to c.2078T>C(p.Ile693Thr) variation of SCN4A gene.

MeSH terms

  • Channelopathies / genetics*
  • Humans
  • Muscle, Skeletal / physiopathology*
  • Mutation
  • NAV1.4 Voltage-Gated Sodium Channel / genetics*
  • Pedigree

Substances

  • NAV1.4 Voltage-Gated Sodium Channel
  • SCN4A protein, human