The evaluation of neutropenia in common variable immune deficiency patients

Expert Rev Clin Immunol. 2019 Nov;15(11):1225-1233. doi: 10.1080/1744666X.2020.1677154. Epub 2019 Oct 15.

Abstract

Objectives: Common variable immunodeficiency is a primary immunodeficiency disease characterized by hypogammaglobulinemia and heterogeneous clinical features. Neutropenia is a rare complication among CVID patients leading to a higher rate of infections and morbidity. Multiple factors (e.g. autoimmunity, infections, drugs and etc.) are found to underlie this complication.Methods: In the present study, demographic, clinical and laboratory data were compared between two groups of CVID patients with and without neutropenia.Results: Frequency of neutropenia was 8.1%. Infectious complications were the most prevalent clinical manifestations regardless of presence of neutropenia. However, candida infection and septicemia were significantly higher in neutropenic patients (p = 0.001 and p = 0.01, respectively). The most prominent clinical phenotypes of CVID patients with neutropenia were polyclonal lymphocytic infiltration and autoimmunity, both being considerably higher compared to the non-neutropenic group (p = 0.04 and p = 0.009, respectively). The mortality rate in neutropenic patients was higher than in patients without neutropenia (61.1 vs. 25.2%, p = 0.004).Conclusion: Although neutropenia is a rare complication among CVID patients, it is associated with frequent and severe clinical complications, including autoimmunity and lymphoproliferative conditions. Also, its accompaniment with higher mortality frequency in CVID patients indicates a need for more precise attention and consideration regarding specific treatment in neutropenic patients.

Keywords: Primary immunodeficiency diseases; autoimmune cytopenia; common variable immunodeficiency; hypersplenism; neutropenia.

Publication types

  • Clinical Trial
  • Research Support, Non-U.S. Gov't
  • Video-Audio Media

MeSH terms

  • Adolescent
  • Adult
  • Child
  • Child, Preschool
  • Common Variable Immunodeficiency* / epidemiology
  • Common Variable Immunodeficiency* / immunology
  • Common Variable Immunodeficiency* / pathology
  • Female
  • Follow-Up Studies
  • Humans
  • Male
  • Neutropenia* / epidemiology
  • Neutropenia* / immunology
  • Neutropenia* / pathology
  • Retrospective Studies