A phase I study of panobinostat and ruxolitinib in patients with primary myelofibrosis (PMF) and post--polycythemia vera/essential thrombocythemia myelofibrosis (post--PV/ET MF)

Leuk Res. 2020 Jan:88:106272. doi: 10.1016/j.leukres.2019.106272. Epub 2019 Nov 16.

Abstract

Ruxolitinib, a selective JAK1/JAK2 inhibitor, is the current first line therapy for myelofibrosis (MF), which reduces symptomatology and splenomegaly, but does not clearly modify disease course. Panobinostat, a histone deacetylase inhibitor, was shown to be safe and tolerable in phase I and II trials and demonstrated clinical activity in approximately a third of treated patients. Combination therapy of ruxolitinib and panobinostat showed synergistic activity in a preclinical MF model, which prompted clinical evaluation of this combination in both ruxolitinib naïve and treated MF patients. Herein, we report the results of an investigator-initiated, dose escalation, phase I trial of ruxolitinib and panobinostat in 15 patients with primary MF and post-polycythemia vera/essential thrombocythemia MF. This combination treatment proved to be safe and tolerable without dose limiting thrombocytopenia and a maximum tolerated dose of both agents in combination was not determined. The majority of patients maintained stable disease with this combination treatment and 40 % attained a clinical improvement (spleen n = 5, anemia n = 1) by modified IWG-MRT at the end of 6 cycles. This is one of the first attempts of rationally designed, JAK inhibitor-based, combination therapy studies and exemplifies the feasibility of such an approach in patients with advanced MF.

Keywords: Myelofibrosis; Panobinostat; Ruxolitinib.

Publication types

  • Clinical Trial, Phase I
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Aged
  • Cohort Studies
  • Dose-Response Relationship, Drug
  • Drug Administration Schedule
  • Drug Therapy, Combination / adverse effects
  • Female
  • Humans
  • Male
  • Maximum Tolerated Dose
  • Middle Aged
  • Nitriles
  • Panobinostat / administration & dosage*
  • Panobinostat / adverse effects*
  • Polycythemia Vera / complications
  • Polycythemia Vera / drug therapy*
  • Primary Myelofibrosis / drug therapy*
  • Primary Myelofibrosis / etiology
  • Pyrazoles / administration & dosage*
  • Pyrazoles / adverse effects*
  • Pyrimidines
  • Thrombocythemia, Essential / complications
  • Thrombocythemia, Essential / drug therapy*
  • Treatment Outcome

Substances

  • Nitriles
  • Pyrazoles
  • Pyrimidines
  • ruxolitinib
  • Panobinostat