Case report of IgG4-related appendiceal disease: A challenging disease

Medicine (Baltimore). 2020 Jun 19;99(25):e20588. doi: 10.1097/MD.0000000000020588.

Abstract

Rationale: Immunoglobulin G4 (IgG4)-related disease is an increasingly recognized immune-mediated entity that can affect virtually every organ system. Depending on the location of the disease, it can present a wide range of clinical manifestations and even mimic malignancies. Appendiceal involvement in patients with IgG4-related disease is particularly rare and very few cases are reported in the literature.

Patient concerns: We report a case of IgG4-related appendiceal disease in a 42-year-old woman who presents with a subacute onset of right lower quadrant abdominal pain.

Diagnosis: Abdominal computed tomography showed a markedly enlarged appendix, raising the concern of malignancy. The diagnosis of IgG4 appendiceal disease was confirmed by postoperative histopathologic and immunohistochemical examination.

Interventions: The patient underwent right hemicolectomy.

Outcomes: After the surgery, the patient had an uneventful recovery and reported a resolution of her symptoms. The serum IgG4 was revaluated 5 days after surgery and returned to its normal values. At the 3-year follow up, the patient had no recurrence of symptoms and her imaging exams remain unremarkable.

Lessons: This study reports the fifth case of IgG4-related appendiceal disease. Increasing awareness of this condition may influence the management of these patients, once patients with IgG4-related disease should be monitored after treatment, due to the risk of recurrence or involvement of other organs.

Publication types

  • Case Reports

MeSH terms

  • Adult
  • Appendix / diagnostic imaging
  • Appendix / pathology*
  • Appendix / surgery
  • Colectomy / methods
  • Diagnosis, Differential
  • Female
  • Humans
  • Imaging, Three-Dimensional
  • Immunoglobulin G / blood
  • Immunoglobulin G4-Related Disease / blood
  • Immunoglobulin G4-Related Disease / diagnosis*
  • Immunoglobulin G4-Related Disease / pathology
  • Immunoglobulin G4-Related Disease / surgery
  • Tomography, X-Ray Computed

Substances

  • Immunoglobulin G