Eagle syndrome after a fracture of complete ossified stylohyoid ligament from indirect trauma treated using local steroid injection: A case report

Medicine (Baltimore). 2020 Jun 19;99(25):e20818. doi: 10.1097/MD.0000000000020818.

Abstract

Rationale: Stylohyoid complex syndrome is characterized by various cervicopharyngeal symptoms related to the ossification and abnormality of the styloid process, stylohyoid ligament, and the lesser horn of the hyoid bone. Eagle syndrome is the most well-known of the spectra of these diseases. Although surgical treatment is considered effective, conservative treatment may be beneficial if symptoms arise because of inflammation of the soft tissues attached to the styloid process or hyoid bone.

Patient concerns: A 68-year-old man presented with pain in the right side of the neck and odynophagia after trauma on his philtrum. He was diagnosed with Eagle syndrome elicited by a fracture from indirect trauma. Despite analgesic medication and physiotherapy, the pain had somewhat relieved but persisted for 1 year.

Diagnosis: Computed tomography revealed complete ossification of the bilateral stylohyoid complex. A fracture was observed in the ampulla on the right side of the neck. One year later, the fracture resolved by complete union.

Interventions: Ultrasonography was performed and abnormal ossification was observed on the right side of the neck. Five milligrams of dexamethasone at a concentration of 1 kg/m was slowly injected into the tender point under ultrasonographic guidance.

Outcomes: The patient reported immediate reduction of pain and was satisfied with the resolution. No recurrence was observed during a 6-month follow-up period.

Lessons: Although traumatic fracture of the ossified ligament elicited the syndrome, the results were satisfactory because the origin of the patient's pain was presumed to arise from inflammatory conditions. This case demonstrates that treatment with local steroid injection may be appropriate for patients who present with pain originating from muscles and ligaments.

Publication types

  • Case Reports

MeSH terms

  • Aged
  • Dexamethasone / administration & dosage
  • Dexamethasone / therapeutic use*
  • Fractures, Bone / complications*
  • Humans
  • Hyoid Bone / injuries*
  • Ligaments, Articular / injuries*
  • Ligaments, Articular / pathology
  • Male
  • Ossification, Heterotopic / diagnosis*
  • Ossification, Heterotopic / drug therapy
  • Ossification, Heterotopic / etiology
  • Temporal Bone / abnormalities*

Substances

  • Dexamethasone

Supplementary concepts

  • Eagle syndrome