Fusion of the COL4A5 Gene With NR2F2-AS1 in a Hemangioma Carrying a t(X;15)(q22;q26) Chromosomal Translocation

Cancer Genomics Proteomics. 2020 Jul-Aug;17(4):383-390. doi: 10.21873/cgp.20197.

Abstract

Background/aim: Hemangiomas are benign neoplastic proliferations of blood vessels. Cytogenetic information on hemangiomas is limited to four tumors with abnormal karyotypes. We report here a solitary chromosomal translocation and its molecular consequence in a hemangioma.

Materials and methods: A cavernous hemangioma was extirpated from the foot of a 62 years old man and genetically studied with cytogenetic and molecular genetic methodologies.

Results: G-Banding analysis of short-term cultured tumor cells yielded the karyotype 46,Y,t(X;15)(q22;q26)[4]/46,XY[12]. RNA sequencing detected fusion of the collagen type IV alpha 5 chain gene (COL4A5 on Xq22.3) with intronic sequences of nuclear receptor subfamily 2 group F member 2 antisense RNA 1 (NR2F2-AS1 on 15q26.2) resulting in a putative COL4A5 truncated protein. The fusion was verified by RT-PCR together with Sanger sequencing and FISH analyses.

Conclusion: The involvement of COL4A5 indicates that some hemangiomas have pathogenetic similarities with other benign tumors such as leiomyomas and subungual exostosis.

Keywords: COL4A5; COL4A5–NR2F2-AS1; Hemangioma; NR2F2-AS1; RNA sequencing; chromosome translocation; cytogenetics; fusion gene; karyotype.

Publication types

  • Case Reports

MeSH terms

  • COUP Transcription Factor II / genetics*
  • Chromosomes, Human, Pair 15 / genetics*
  • Chromosomes, Human, X / genetics*
  • Collagen Type IV / genetics*
  • Hemangioma / genetics
  • Hemangioma / pathology*
  • Humans
  • Male
  • Middle Aged
  • Oncogene Proteins, Fusion / genetics*
  • RNA, Antisense / genetics*
  • Translocation, Genetic*

Substances

  • COL4A5 protein, human
  • COUP Transcription Factor II
  • Collagen Type IV
  • NR2F2 protein, human
  • Oncogene Proteins, Fusion
  • RNA, Antisense