Persisting Muscle Dysfunction in Cushing's Syndrome Despite Biochemical Remission

J Clin Endocrinol Metab. 2020 Dec 1;105(12):e4490-e4498. doi: 10.1210/clinem/dgaa625.

Abstract

Context: Glucocorticoid-induced myopathy is a characteristic symptom of endogenous Cushing's syndrome (CS). Its long-term outcome is largely unknown.

Objective: To evaluate long-term muscle function following the remission of endogenous CS.

Study design: Observational longitudinal cohort study.

Setting: Tertiary care hospitals and a specialized outpatient clinic.

Patients: As part of the prospective multicenter German Cushing's Registry, we assessed muscle strength in patients with overt endogenous CS. We studied the patients at the time of diagnosis (n = 88), after 6 months (n = 69), and thereafter annually, following surgical remission over a period of up to 4 years (1 year: n = 55; 2 years: n = 34; 3 years: n = 29; 4 years: n = 22). Muscle function was evaluated by hand grip strength and by chair rising test.

Results: Grip strength was decreased to 83% of normal controls (100%) at the time of diagnosis. It further decreased to 71% after 6 months in remission (P ≤ 0.001) and showed no improvement during further follow-up compared with baseline. Chair rising test performance improved initially (8 seconds at baseline vs 7 seconds after 6 months, P = 0.004) but remained at this reduced level thereafter (7 seconds after 3 years vs 5 seconds in controls, P = 0.038). In multivariate analysis, we identified, as predictors for long-term muscle dysfunction, age, waist-to-hip ratio, and hemoglobin A1c at baseline. Furthermore, muscle strength during follow-up was strongly correlated with quality of life.

Conclusion: This study shows that CS-associated myopathy does not spontaneously resolve during remission. This calls for action to identify effective interventions to improve muscle dysfunction in this setting.

Keywords: ACTH; cortisol; diabetes; hypercortisolism; muscle; sarcopenia.

Publication types

  • Multicenter Study
  • Observational Study
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Adult
  • Biomarkers / analysis
  • Case-Control Studies
  • Cohort Studies
  • Cushing Syndrome / complications*
  • Cushing Syndrome / diagnosis
  • Cushing Syndrome / physiopathology
  • Cushing Syndrome / surgery*
  • Female
  • Germany
  • Hand Strength / physiology
  • Humans
  • Longitudinal Studies
  • Male
  • Middle Aged
  • Muscle Strength / physiology
  • Muscular Diseases / diagnosis
  • Muscular Diseases / etiology*
  • Muscular Diseases / physiopathology
  • Muscular Diseases / surgery
  • Prognosis
  • Quality of Life
  • Remission Induction
  • Time Factors
  • Treatment Outcome

Substances

  • Biomarkers