Development and validation of a potent and specific inhibitor for the CLC-2 chloride channel

Proc Natl Acad Sci U S A. 2020 Dec 22;117(51):32711-32721. doi: 10.1073/pnas.2009977117. Epub 2020 Dec 4.

Abstract

CLC-2 is a voltage-gated chloride channel that is widely expressed in mammalian tissues. In the central nervous system, CLC-2 appears in neurons and glia. Studies to define how this channel contributes to normal and pathophysiological function in the central nervous system raise questions that remain unresolved, in part due to the absence of precise pharmacological tools for modulating CLC-2 activity. Herein, we describe the development and optimization of AK-42, a specific small-molecule inhibitor of CLC-2 with nanomolar potency (IC50 = 17 ± 1 nM). AK-42 displays unprecedented selectivity (>1,000-fold) over CLC-1, the closest CLC-2 homolog, and exhibits no off-target engagement against a panel of 61 common channels, receptors, and transporters expressed in brain tissue. Computational docking, validated by mutagenesis and kinetic studies, indicates that AK-42 binds to an extracellular vestibule above the channel pore. In electrophysiological recordings of mouse CA1 hippocampal pyramidal neurons, AK-42 acutely and reversibly inhibits CLC-2 currents; no effect on current is observed on brain slices taken from CLC-2 knockout mice. These results establish AK-42 as a powerful tool for investigating CLC-2 neurophysiology.

Keywords: CLC-2; chloride channel; inhibitor.

Publication types

  • Research Support, N.I.H., Extramural
  • Research Support, Non-U.S. Gov't
  • Validation Study

MeSH terms

  • Animals
  • Binding Sites
  • CHO Cells
  • CLC-2 Chloride Channels
  • Cell Line
  • Chloride Channels / antagonists & inhibitors*
  • Chloride Channels / chemistry*
  • Chloride Channels / genetics
  • Chloride Channels / metabolism
  • Cricetulus
  • Dose-Response Relationship, Drug
  • Drug Evaluation, Preclinical / methods
  • Hippocampus / metabolism
  • Humans
  • Mice, Inbred C57BL
  • Mice, Knockout
  • Molecular Docking Simulation
  • Organ Culture Techniques
  • Patch-Clamp Techniques
  • Pyramidal Cells / drug effects
  • Pyramidal Cells / metabolism
  • Small Molecule Libraries / chemistry*
  • Small Molecule Libraries / metabolism
  • Small Molecule Libraries / pharmacology*
  • Structure-Activity Relationship

Substances

  • CLC-2 Chloride Channels
  • Chloride Channels
  • Small Molecule Libraries