Multidisciplinary diagnosis and treatment of recurrent follicular dendritic cell sarcoma in abdomen: A case report

Medicine (Baltimore). 2020 Dec 18;99(51):e23588. doi: 10.1097/MD.0000000000023588.

Abstract

Rationale: Follicular dendritic cell sarcoma (FDCS) is a rare malignant tumor derived from follicular dendritic cells, and is often associated with Castleman disease. Here we present a rare case of paraneoplastic pemphigus (PNP) with FDCS which required multidisciplinary approach for the diagnosis and treatment.

Patient concerns: A 28-year-old Chinese female had FDCS recurrence, and primary clinical manifestation was PNP.

Diagnoses: PNP with FDCS.

Interventions: The patient received gamma globulin infusion, took anlotinib, and underwent plasma exchange therapy.

Outcomes: The skin lesions recovered and there was no evidence of tumor recurrence.

Lessons: The diagnosis and management of PNP with FDCS require close cooperation among surgeons, dermatologists, hematologists, otolaryngologists, oncologists, radiologists, pathologists, and respiratory doctors. The interesting clinical manifestations of this patient provide a multifaceted approach to the investigation of the interactions among FDCS, Castleman disease, and PNP.

Publication types

  • Case Reports

MeSH terms

  • Abdomen / pathology*
  • Adult
  • Dendritic Cell Sarcoma, Follicular / complications*
  • Dendritic Cell Sarcoma, Follicular / diagnosis
  • Dendritic Cell Sarcoma, Follicular / therapy
  • Female
  • Humans
  • Paraneoplastic Syndromes / complications*
  • Paraneoplastic Syndromes / diagnosis
  • Paraneoplastic Syndromes / therapy
  • Pemphigus / complications*
  • Pemphigus / diagnosis
  • Pemphigus / therapy