Central Nervous System Histoplasma-Associated Post-infectious Inflammatory Response Syndrome (Histo-PIIRS)

J Clin Immunol. 2021 Apr;41(3):545-551. doi: 10.1007/s10875-020-00954-9. Epub 2021 Jan 2.

Abstract

We present a case of central nervous system (CNS) histoplasmosis in a previously healthy adult with hepatitis C (HCV) presenting with neurological symptoms refractory to antifungal therapy and ventriculoperitoneal (VP) shunting 4 months after initial diagnosis. Persistent symptoms were thought to be inflammatory rather than infectious given negative cerebrospinal fluid (CSF) and serum fungal antigens. The patient promptly improved after initiation of corticosteroid therapy. Elevated CSF cytokines and regional enhancement on brain MRI resolved with corticosteroid treatment. This is the first case of Histoplasma-associated post-infectious inflammatory response syndrome (Histo-PIIRS) documented by CSF cytokine reduction in response to corticosteroid therapy.

Keywords: Fungal meningitis; central nervous system; histoplasma; inflammation.

Publication types

  • Case Reports
  • Research Support, N.I.H., Extramural
  • Research Support, N.I.H., Intramural
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Biomarkers
  • Central Nervous System Fungal Infections / complications*
  • Central Nervous System Fungal Infections / microbiology
  • Cytokines / metabolism
  • Histoplasmosis / complications*
  • Histoplasmosis / microbiology
  • Humans
  • Magnetic Resonance Imaging
  • Male
  • Neuroinflammatory Diseases / diagnosis*
  • Neuroinflammatory Diseases / etiology*
  • Neuroinflammatory Diseases / therapy
  • Symptom Assessment
  • Syndrome
  • Young Adult

Substances

  • Biomarkers
  • Cytokines