Molecular Alterations in Sporadic and SOD1-ALS Immortalized Lymphocytes: Towards a Personalized Therapy

Int J Mol Sci. 2021 Mar 16;22(6):3007. doi: 10.3390/ijms22063007.

Abstract

Amyotrophic lateral sclerosis (ALS) is a fatal neurological condition where motor neurons (MNs) degenerate. Most of the ALS cases are sporadic (sALS), whereas 10% are hereditarily transmitted (fALS), among which mutations are found in the gene that codes for the enzyme superoxide dismutase 1 (SOD1). A central question in ALS field is whether causative mutations display selective alterations not found in sALS patients, or they converge on shared molecular pathways. To identify specific and common mechanisms for designing appropriate therapeutic interventions, we focused on the SOD1-mutated (SOD1-ALS) versus sALS patients. Since ALS pathology involves different cell types other than MNs, we generated lymphoblastoid cell lines (LCLs) from sALS and SOD1-ALS patients and healthy donors and investigated whether they show changes in oxidative stress, mitochondrial dysfunction, metabolic disturbances, the antioxidant NRF2 pathway, inflammatory profile, and autophagic flux. Both oxidative phosphorylation and glycolysis appear to be upregulated in lymphoblasts from sALS and SOD1-ALS. Our results indicate significant differences in NRF2/ARE pathway between sALS and SOD1-ALS lymphoblasts. Furthermore, levels of inflammatory cytokines and autophagic flux discriminate between sALS and SOD1-ALS lymphoblasts. Overall, different molecular mechanisms are involved in sALS and SOD1-ALS patients and thus, personalized medicine should be developed for each case.

Keywords: NRF2; amyotrophic lateral sclerosis; autophagy; bioenergetic metabolism; inflammation; lymphoblast; oxidative stress.

MeSH terms

  • Acids / metabolism
  • Aged
  • Aged, 80 and over
  • Amyotrophic Lateral Sclerosis / enzymology*
  • Amyotrophic Lateral Sclerosis / genetics
  • Amyotrophic Lateral Sclerosis / immunology*
  • Autophagy / genetics
  • Cell Line, Transformed
  • Energy Metabolism
  • Female
  • Heterozygote
  • Humans
  • Lymphocytes / immunology*
  • Magnetic Resonance Spectroscopy
  • Male
  • Metabolomics
  • Middle Aged
  • Mutation / genetics*
  • NF-E2-Related Factor 2 / metabolism
  • Oxidative Stress
  • Oxygen Consumption
  • Precision Medicine*
  • RNA, Messenger / genetics
  • RNA, Messenger / metabolism
  • Reactive Oxygen Species / metabolism
  • Signal Transduction
  • Superoxide Dismutase-1 / genetics*
  • Superoxide Dismutase-1 / metabolism
  • Thiobarbituric Acid Reactive Substances / metabolism

Substances

  • Acids
  • NF-E2-Related Factor 2
  • NFE2L2 protein, human
  • RNA, Messenger
  • Reactive Oxygen Species
  • Thiobarbituric Acid Reactive Substances
  • Superoxide Dismutase-1