Hyperactivity is a Core Endophenotype of Elevated Neuregulin-1 Signaling in Embryonic Glutamatergic Networks

Schizophr Bull. 2021 Aug 21;47(5):1409-1420. doi: 10.1093/schbul/sbab027.

Abstract

The neuregulin 1 (NRG1) ErbB4 module is at the core of an "at risk" signaling pathway in schizophrenia. Several human studies suggest hyperstimulation of NRG1-ErbB4 signaling as a plausible pathomechanism; however, little is known about the significance of stage-, brain area-, or neural cell type-specific NRG1-ErbB4 hyperactivity for disease-relevant brain endophenotypes. To address these spatiotemporal aspects, we generated transgenic mice for Cre recombinase-mediated overexpression of cystein-rich domain (CRD) NRG1, the most prominent NRG1 isoform in the brain. A comparison of "brain-wide" vs cell type-specific CRD-NRG1 overexpressing mice revealed that pathogenic CRD-NRG1 signals for ventricular enlargement and neuroinflammation originate outside glutamatergic neurons and suggests a subcortical function of CRD-NRG1 in the control of body weight. Embryonic onset of CRD-NRG1 in glutamatergic cortical networks resulted in reduced inhibitory neurotransmission and locomotor hyperactivity. Our findings identify ventricular enlargement and locomotor hyperactivity, 2 main endophenotypes of schizophrenia, as specific consequences of spatiotemporally distinct expression profiles of hyperactivated CRD-NRG1 signaling.

Keywords: ErbB4 receptor; conditional transgenic mice; schizophrenia; ventricular enlargement.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Animals
  • Behavior, Animal / physiology
  • Brain* / metabolism
  • Brain* / physiopathology
  • Disease Models, Animal
  • Embryo, Mammalian
  • Endophenotypes*
  • Glutamic Acid / metabolism*
  • Mice
  • Mice, Inbred C57BL
  • Mice, Transgenic
  • Nerve Net* / metabolism
  • Nerve Net* / physiopathology
  • Neuregulin-1 / metabolism*
  • Psychomotor Agitation* / metabolism
  • Psychomotor Agitation* / physiopathology
  • Receptor, ErbB-4 / metabolism*
  • Schizophrenia* / metabolism
  • Schizophrenia* / physiopathology
  • Signal Transduction / physiology

Substances

  • Neuregulin-1
  • Nrg1 protein, mouse
  • Glutamic Acid
  • Erbb4 protein, mouse
  • Receptor, ErbB-4