Clear Cell Carcinoma in the Oral Cavity with Three Novel Types of EWSR1-ATF1 Translocation: A Case Report

Head Neck Pathol. 2022 Jun;16(2):560-566. doi: 10.1007/s12105-021-01356-y. Epub 2021 Jul 12.

Abstract

Clear cell carcinoma (CCC) is a rare epithelial malignant tumor of the salivary glands. It is characterized by tumor cells with clear cytoplasm, hyalinized stroma, and most importantly the fusion genes EWSR1-ATF1, EWSR1-CREM, and EWSR1-PLAG1. Break-apart FISH has been performed for multiple CCC cases, but direct sequencing analysis has been performed in relatively few. Herein, we report an interesting case of CCC harboring three EWSR1-ATF1 translocations: EWSR1 exon 8-ATF1 exon 4, EWSR1 exon 7-ATF1 exon 4, and EWSR1 exon 7-ATF1 exon 5. This case indicates the possibility of independent EWSR1-ATF1 gene translocations, and could provide insight into CCC tumorgenesis.

Keywords: ATF1; Clear cell carcinoma; EWSR1; Hyalinizing clear cell carcinoma; Salivary duct tumor.

Publication types

  • Case Reports

MeSH terms

  • Adenocarcinoma, Clear Cell* / genetics
  • Exons
  • Humans
  • Mouth
  • Oncogene Proteins, Fusion* / genetics
  • RNA-Binding Protein EWS / genetics
  • Transcription Factors / genetics

Substances

  • EWSR1 protein, human
  • EWSR1-ATF1 fusion protein, human
  • Oncogene Proteins, Fusion
  • RNA-Binding Protein EWS
  • Transcription Factors