An open label randomized controlled trial of tamoxifen combined with amphotericin B and fluconazole for cryptococcal meningitis

Elife. 2021 Sep 28:10:e68929. doi: 10.7554/eLife.68929.

Abstract

Background: Cryptococcal meningitis has high mortality. Flucytosine is a key treatment but is expensive and rarely available. The anticancer agent tamoxifen has synergistic anti-cryptococcal activity with amphotericin in vitro. It is off-patent, cheap, and widely available. We performed a trial to determine its therapeutic potential.

Methods: Open label randomized controlled trial. Participants received standard care - amphotericin combined with fluconazole for the first 2 weeks - or standard care plus tamoxifen 300 mg/day. The primary end point was Early Fungicidal Activity (EFA) - the rate of yeast clearance from cerebrospinal fluid (CSF). Trial registration https://clinicaltrials.gov/ct2/show/NCT03112031.

Results: Fifty patients were enrolled (median age 34 years, 35 male). Tamoxifen had no effect on EFA (-0.48log10 colony-forming units/mL/CSF control arm versus -0.49 tamoxifen arm, difference -0.005log10CFU/ml/day, 95% CI: -0.16, 0.15, p=0.95). Tamoxifen caused QTc prolongation.

Conclusions: High-dose tamoxifen does not increase the clearance rate of Cryptococcus from CSF. Novel, affordable therapies are needed.

Funding: The trial was funded through the Wellcome Trust Asia Programme Vietnam Core Grant 106680 and a Wellcome Trust Intermediate Fellowship to JND grant number WT097147MA.

Keywords: HIV; Viet Nam; cryptococcal meningitis; cryptococcus gattii; cryptococcus neoformans; infectious disease; medicine; microbiology; randomised controlled trial.

Publication types

  • Randomized Controlled Trial
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Adult
  • Amphotericin B / therapeutic use*
  • Antifungal Agents / therapeutic use
  • Cryptococcus neoformans / drug effects*
  • Drug Therapy, Combination
  • Female
  • Fluconazole / therapeutic use*
  • Humans
  • Long QT Syndrome / chemically induced
  • Male
  • Meningitis, Cryptococcal / cerebrospinal fluid
  • Meningitis, Cryptococcal / drug therapy*
  • Meningitis, Cryptococcal / metabolism
  • Tamoxifen / adverse effects
  • Tamoxifen / therapeutic use*

Substances

  • Antifungal Agents
  • Tamoxifen
  • Amphotericin B
  • Fluconazole

Associated data

  • ClinicalTrials.gov/NCT03112031