The histone demethylase Lsd1 regulates multiple repressive gene programs during T cell development

J Exp Med. 2021 Dec 6;218(12):e20202012. doi: 10.1084/jem.20202012. Epub 2021 Nov 2.

Abstract

Analysis of the transcriptional profiles of developing thymocytes has shown that T lineage commitment is associated with loss of stem cell and early progenitor gene signatures and the acquisition of T cell gene signatures. Less well understood are the epigenetic alterations that accompany or enable these transcriptional changes. Here, we show that the histone demethylase Lsd1 (Kdm1a) performs a key role in extinguishing stem/progenitor transcriptional programs in addition to key repressive gene programs during thymocyte maturation. Deletion of Lsd1 caused a block in late T cell development and resulted in overexpression of interferon response genes as well as genes regulated by the Gfi1, Bcl6, and, most prominently, Bcl11b transcriptional repressors in CD4+CD8+ thymocytes. Transcriptional overexpression in Lsd1-deficient thymocytes was not always associated with increased H3K4 trimethylation at gene promoters, indicating that Lsd1 indirectly affects the expression of many genes. Together, these results identify a critical function for Lsd1 in the epigenetic regulation of multiple repressive gene signatures during T cell development.

Publication types

  • Research Support, N.I.H., Intramural

MeSH terms

  • Animals
  • Cell Lineage / genetics
  • DNA-Binding Proteins / genetics
  • Epigenesis, Genetic*
  • Gene Expression Regulation
  • Histone Demethylases / genetics*
  • Histone Demethylases / metabolism
  • Histones / genetics
  • Histones / metabolism
  • Mice
  • Mice, Mutant Strains
  • Mice, Transgenic
  • Promoter Regions, Genetic
  • Proto-Oncogene Proteins c-bcl-6 / genetics
  • Repressor Proteins / genetics
  • T-Lymphocytes / physiology*
  • Thymocytes / cytology*
  • Thymocytes / physiology
  • Transcription Factors / genetics
  • Tumor Suppressor Proteins / genetics

Substances

  • Bcl11b protein, mouse
  • Bcl6 protein, mouse
  • DNA-Binding Proteins
  • Gfi1 protein, mouse
  • Histones
  • Proto-Oncogene Proteins c-bcl-6
  • Repressor Proteins
  • Transcription Factors
  • Tumor Suppressor Proteins
  • histone H3 trimethyl Lys4
  • Histone Demethylases
  • KDM1a protein, mouse