KBG syndrome in a Chinese population: A case series

Am J Med Genet A. 2022 Jun;188(6):1693-1699. doi: 10.1002/ajmg.a.62688. Epub 2022 Feb 17.

Abstract

KBG syndrome (OMIM #148050) is an autosomal dominant neurodevelopmental disorder characterized by the presence of macrodontia of the permanent central upper incisors, characteristic facial features, delay in development, intellectual disability, short stature, and various skeletal abnormalities. Over 200 affected individuals have been described worldwide, though underdiagnosis is suspected because the characteristic features are variably present and affected individuals can have a mild phenotype. This case series provides a summary of the clinical and molecular characteristics of 10 Chinese KBG syndrome patients recruited from a single center. To our knowledge, this is the first case series for Chinese KBG patients. This case series aimed at exploring potential ethnicity-related variability in KBG syndrome.

Keywords: ANKRD11; Chinese; KBG syndrome; macrodontia.

MeSH terms

  • Abnormalities, Multiple* / diagnosis
  • Abnormalities, Multiple* / genetics
  • Bone Diseases, Developmental* / diagnosis
  • Bone Diseases, Developmental* / genetics
  • China / epidemiology
  • Comparative Genomic Hybridization
  • Facies
  • Humans
  • Intellectual Disability* / diagnosis
  • Intellectual Disability* / genetics
  • Phenotype
  • Repressor Proteins / genetics
  • Tooth Abnormalities* / diagnosis
  • Tooth Abnormalities* / genetics

Substances

  • Repressor Proteins

Supplementary concepts

  • KBG syndrome