Paediatric astroblastoma-like neuroepithelial tumour of the spinal cord with a MAMLD1-BEND2 rearrangement

Neuropathol Appl Neurobiol. 2022 Aug;48(5):e12814. doi: 10.1111/nan.12814. Epub 2022 Apr 10.

Abstract

Astroblastomas are neuroepithelial tumours defined by the presence of MN1 rearrangement and are typically located in the cerebral hemispheres. Rare cases of astroblastoma-like tumours carrying an EWSR1-BEND2 fusion have been recently described in the brain stem and spinal cord. We report a paediatric case of neuroepithelial astroblastoma-like tumour occurring in the spine and carrying a novel MAMLD1-BEND2 fusion. We believe that our case aligns with the rare astroblastoma-like tumours with EWSR1-BEND2 fusion, in terms of non-hemispheric location, pathology, methylation profile and activation of BEND2 transcription. Whether they may represent a distinct entity or a variant of MN1-altered astroblastoma is not clear.

Keywords: EWSR1-BEND2 fusion; MAMLD1-BEND2 fusion; astroblastoma-like neuroepithelial tumour; high grade glioma; spinal cord.

Publication types

  • Case Reports
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Brain Neoplasms* / pathology
  • Child
  • Chromosome Aberrations
  • DNA-Binding Proteins
  • Humans
  • Neoplasms, Neuroepithelial* / genetics
  • Neoplasms, Neuroepithelial* / pathology
  • Nuclear Proteins
  • Spinal Cord Neoplasms* / genetics
  • Trans-Activators
  • Transcription Factors
  • Tumor Suppressor Proteins / genetics

Substances

  • DNA-Binding Proteins
  • MAMLD1 protein, human
  • Nuclear Proteins
  • Trans-Activators
  • Transcription Factors
  • Tumor Suppressor Proteins