Detection of a new deleterious SGCE gene variant in Moroccan family with inherited myoclonus-dystonia

Clin Case Rep. 2022 Mar 17;10(3):e05568. doi: 10.1002/ccr3.5568. eCollection 2022 Mar.

Abstract

Myoclonus-dystonia (M-D) is a pleiotropic neuropsychiatric disorder with autosomal dominant mode of inheritance with variable severity and incomplete penetrance. Pathogenic variants in ξ-sarcoglycan gene SGCE are the most frequently known genetic cause of M-D with maternal imprinting, and in most cases, a symptomatic individual inherits the pathogenic variant from his or her father. This work reported a missense mutation c.662G> T inherited in the M-D Moroccan family described for the first time, which is deleterious based on protein modeling analysis.

Keywords: Morocco; SGCE gene; c.662G>T mutation; familial myoclonus–dystonia; modeling.

Publication types

  • Case Reports