Repurposing antiparasitic antimonials to noncovalently rescue temperature-sensitive p53 mutations

Cell Rep. 2022 Apr 12;39(2):110622. doi: 10.1016/j.celrep.2022.110622.

Abstract

The tumor suppressor p53 is inactivated by over hundreds of heterogenous mutations in cancer. Here, we purposefully selected phenotypically reversible temperature-sensitive (TS) p53 mutations for pharmacological rescue with thermostability as the compound-screening readout. This rational screening identified antiparasitic drug potassium antimony tartrate (PAT) as an agent that can thermostabilize the representative TS mutant p53-V272M via noncovalent binding. PAT met the three basic criteria for a targeted drug: availability of a co-crystal structure, compatible structure-activity relationship, and intracellular target specificity, consequently exhibiting antitumor activity in a xenograft mouse model. At the antimony dose in clinical antiparasitic therapy, PAT effectively and specifically rescued p53-V272M in patient-derived primary leukemia cells in single-cell RNA sequencing. Further scanning of 815 frequent p53-missense mutations identified 65 potential PAT-treatable mutations, most of which were temperature sensitive. These results lay the groundwork for repurposing noncovalent antiparasitic antimonials for precisely treating cancers with the 65 p53 mutations.

Trial registration: ClinicalTrials.gov NCT04869475 NCT04489706 NCT04695223 NCT04906031.

Keywords: CP: Cancer; antimonials; drug repurposing; precision medicine; temperature-sensitive mutations; tumor suppressor p53.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Animals
  • Antimony / metabolism
  • Antimony / pharmacology
  • Antimony / therapeutic use
  • Antiparasitic Agents
  • Drug Repositioning
  • Humans
  • Mice
  • Mutation / genetics
  • Neoplasms* / genetics
  • Temperature
  • Tumor Suppressor Protein p53* / metabolism

Substances

  • Antiparasitic Agents
  • Tumor Suppressor Protein p53
  • Antimony

Associated data

  • ClinicalTrials.gov/NCT04869475
  • ClinicalTrials.gov/NCT04489706
  • ClinicalTrials.gov/NCT04695223
  • ClinicalTrials.gov/NCT04906031
  • ChiCTR/ChiCTR2000032269