Isolated psychiatric presentation of cobalamin C type disorder with novel mutation in middle childhood: A case report

Asian J Psychiatr. 2022 Jul:73:103131. doi: 10.1016/j.ajp.2022.103131. Epub 2022 Apr 25.

Abstract

A 9-year-old boy presented with abnormal behavior for six months. He had unprovoked aggressive behavior, and occasional self-inflicting behavior. He also had decreased appetite, anhedonia, apathy, reduced sleep, low energy, motivation, and poor interaction with parents and peers. He had mild cognitive impairment, below-average intelligence, moderate depression, and mild psychotic symptoms on assessment with appropriate scales. He had macrocytic anemia with low vitamin B12 levels. Nextgeneration sequencing revealed a novel mutation of Leu116Pro of the MMACHC gene, suggestive of combined methylmalonic aciduria and homocystinuria (cblC type). Timely initiation of therapy can change the long-term neurological outcome.

Keywords: Combined methylmalonic aciduria and homocystinuria; Neurometabolic disorder; Neuropsychiatric symptoms; Novel mutation.

Publication types

  • Case Reports

MeSH terms

  • Carrier Proteins / genetics
  • Child
  • Homocystinuria* / complications
  • Homocystinuria* / diagnosis
  • Homocystinuria* / genetics
  • Humans
  • Male
  • Mutation
  • Oxidoreductases / genetics
  • Vitamin B 12*

Substances

  • Carrier Proteins
  • MMACHC protein, human
  • Oxidoreductases
  • Vitamin B 12