Persistence of persistent pulmonary hypertension of the newborn: A case of de novo TBX4 variant

Pulm Circ. 2022 Jul 1;12(3):e12108. doi: 10.1002/pul2.12108. eCollection 2022 Jul.

Abstract

We present a case of a late preterm infant placed on extracorporeal life support in the first day of life for persistent pulmonary hypertension of the newborn. Developmental arrest, pulmonary vascular hypertensive changes, and pulmonary interstitial glycogenosis were present on lung biopsy at 7 weeks of age. Pulmonary hypertension has persisted through childhood. Genetic testing at 8 years identified a novel mutation in TBX4.

Keywords: genetics; neonatal lung disease; pediatrics; pulmonary arterial hypertension.

Publication types

  • Case Reports