ANCA-negative microscopic polyangiitis with neuromuscular involvement: When pathology could make the difference

Clin Neurol Neurosurg. 2023 Feb:225:107573. doi: 10.1016/j.clineuro.2022.107573. Epub 2022 Dec 24.

Abstract

Microscopic polyangiitis (MPA) is a necrotizing small vessel vasculitis with little or absent immune deposits (pauci-immune vasculitis), usually associated with the presence of antineutrophil cytoplasmic autoantibodies (ANCA) and a wide spectrum of organ manifestations. In our report we describe the case of a 74-year-old Asian man, who rapidly developed lower limb weakness and impaired renal and pulmonary functions. ANCA detection remained borderline throughout the disease course. Electrophysiological and instrumental studies revealed a picture of neuromuscular involvement; renal and muscle biopsies disclosed a small vessel vasculitis. He was started on a targeted immunosuppressive combination therapy and his clinical status progressively improved. In the framework of a multi-organ disease, microscopic polyangiitis should be considered as a differential diagnosis in case of acute/subacute onset of muscle weakness, even in the absence of ANCA detection.

Keywords: ANCA-associated vasculitis; Biopsy; Lower limb weakness; Microscopic polyangiitis; Polyneuropathy.

Publication types

  • Case Reports

MeSH terms

  • Aged
  • Antibodies, Antineutrophil Cytoplasmic
  • Disease Progression
  • Granulomatosis with Polyangiitis* / drug therapy
  • Humans
  • Immunosuppressive Agents / therapeutic use
  • Male
  • Microscopic Polyangiitis* / complications
  • Microscopic Polyangiitis* / diagnosis
  • Microscopic Polyangiitis* / drug therapy

Substances

  • Antibodies, Antineutrophil Cytoplasmic
  • Immunosuppressive Agents