Fungal Keratitis and Corneal Perforation as a Rare Complication of Corneal Collagen Cross-Linking Treatment

Cornea. 2023 Sep 1;42(9):1179-1182. doi: 10.1097/ICO.0000000000003270. Epub 2023 Mar 3.

Abstract

Purpose: The aim of this study was to report a case of fungal keratitis with subsequent corneal perforation after corneal collagen cross-linking (CXL) treatment performed for keratoconus.

Case report: A 20-year-old woman presented with redness and discharge in the left eye. She had a history of bilateral CXL procedure performed for keratoconus elsewhere 4 days earlier. The visual acuity was hand motion in the left eye. Slit-lamp examination revealed extended corneal melting with surrounding infiltrates. The patient was hospitalized, and corneal epithelial scraping samples were sent for microbiological assessment. In the meantime, empirical antibiotic therapy (fortified topical antibiotics: vancomycin 50 mg/mL, ceftazidime 50 mg/mL, and fluconazole 2 mg/mL q1 hour) was initiated. In direct microscopy of the corneal scraping, septate hyaline fungal hyphae were detected and topical fluconazole was switched to topical voriconazole (10 mg/mL). Three days after hospitalization, corneal melting progressed to perforation and corneal suturing with 10-0 monofilament was performed to reform the anterior chamber. Complete resolution of keratitis with residual scarring was noticed in 2 weeks. Three months later, penetrating keratoplasty was performed to obtain better visual acuity.

Conclusions: CXL with riboflavin has become a common procedure to prevent keratoconus progression by strengthening the biomechanical specialties of the cornea. Although the treatment itself has been used in the management of microbial keratitis and related corneal melting, fungal keratitis and corneal perforation after a CXL procedure for keratoconus might also be detected. Clinicians should be aware of this rare but devastating complication of CXL treatment and start prompt treatment when suspected.

Publication types

  • Case Reports

MeSH terms

  • Adult
  • Corneal Cross-Linking
  • Corneal Perforation* / chemically induced
  • Corneal Perforation* / diagnosis
  • Corneal Perforation* / therapy
  • Corneal Ulcer* / complications
  • Corneal Ulcer* / diagnosis
  • Corneal Ulcer* / drug therapy
  • Cross-Linking Reagents / therapeutic use
  • Eye Infections, Fungal* / diagnosis
  • Eye Infections, Fungal* / drug therapy
  • Female
  • Fluconazole / therapeutic use
  • Humans
  • Keratitis* / microbiology
  • Keratoconus* / complications
  • Keratoconus* / drug therapy
  • Photosensitizing Agents / therapeutic use
  • Riboflavin / therapeutic use
  • Ultraviolet Rays
  • Young Adult

Substances

  • Photosensitizing Agents
  • Fluconazole
  • Riboflavin
  • Cross-Linking Reagents

Supplementary concepts

  • Keratoconus 4